Research

Publications & Contributions

Ongoing Research

Elucidating translational aberrations resulting from IGHMBP2 mutations

Sarah Hurt, Gangadhar Vadla, Christian Lorson, and Monique Lorson

Target: Molecular Therapy

Understanding the function of the IGHMBP2-ABT1 interaction and its role in SMARD1/CMT2S

Sarah Hurt, Gangadhar Vadla, Christian Lorson, and Monique Lorson

Target: Cell

Publications

Subtle cellular phenotypes inform pathological and benign genetic mutants in the Iduronidase-2-Sulfatase Gene

BioRxiv, April 2025

Authors: Viswanathan A, Elia S, Le SQ, Hurt S, Balraj Doray, Jason Waligorski, Kylan Kelley, William Buchser, Patricia Dickson

As with most enzyme-storage disorders, DNA testing at an early age is critical for identifying genetic variants and their impact on disease burden. Still, most variants in genes such as Iduronate-2-sulfatase (IDS) are Variants of Uncertain Significance (VUS). In patients presenting with Hunter Syndrome, clinical testing for IDS enzyme activity has been the mainstay to determine whether a variant is likely damaging. This study developed an image-based assay using genome-engineered cells with IDS mutations to identify if a specific mutation causes lysosomal and membrane disruptions that characterize the disease. Overall, these cell-based lysosomal and membrane phenotypes may be key to quickly and accurately profiling clinical variants in the IDS gene.

View Paper

Specific antibodies to recombinant human alpha-L-iduronidase prevent disease correction in cortical bone in mucopolysaccharidosis I mice

Molecular Therapy: Methods & Clinical Development, March 2025

Authors: Hurt SC, Le SQ, Kan S, Bui QD, Brodt MD, Dickson PI

Mucopolysaccharidosis I (MPS I) is a lysosomal storage disorder resulting from a deficiency in the enzyme α-L-iduronidase (IDUA). The study hypothesized that the failure of ERT to address skeletal disease in MPS I might be due to the development of anti-IDUA antibodies. The findings indicated that mice receiving ERT along with IRIG exhibited less disease correction in their cortical bone compared to those receiving ERT alone. This suggests that the development of anti-IDUA antibodies can impair the effectiveness of ERT by altering the tissue distribution of the enzyme, particularly in skeletal disease.

View Paper

Combining angiotensin receptor blockade and enzyme replacement therapy for vascular disease in mucopolysaccharidosis type I

Molecular Genetics and Metabolism Reports, December 2023

Authors: Hurt SC, Vera MU, Le SQ, Kan S, Bui Q, Dickson PI

Vascular involvement in the genetic disorder mucopolysaccharidosis type I (MPS I) has features of atherosclerotic disease near branch points of arterial vasculature, such as intimal thickening with disruption of the internal elastic lamina, and proliferation of macrophages and myofibroblasts. Inflammatory pathways are implicated in the pathogenesis of vascular disease in MPS I animal models, evidenced by cytokines like CD18 and TGF-β within arterial plaques. Here, we combined losartan with the standard therapy for MPS I, enzyme replacement therapy (ERT), to measure effects on cytokines in serum and aortic vasculature. The observations suggest that losartan may impact inflammatory cascades due to MPS I and may also blunt inflammation in combination with ERT.

View Paper

Mucopolysaccharidoses type I gene therapy

Journal of Inherited Metabolic Disease, September 2021

Authors: Hurt SC, Dickson PI, Curiel DT

Mucopolysaccharidoses type I (MPS I) is an inherited metabolic disease characterized by a malfunction of the α-l-iduronidase (IDUA) enzyme leading to the storage of glycosaminoglycans in the lysosomes. This disease has longtime been studied as a therapeutic target for those studying gene therapy and many studies have been done using various vectors to deliver the IDUA gene for corrective treatment. Additionally, the recent modifications to adenoviral vectors leading them to target the vascular endothelium minimizing the risk of hepatotoxicity could lead to them being a viable option for MPS I gene therapy when coupled with gene editing technologies like CRISPR/Cas9.

View Paper

Transcriptome and Organellar Genome Sequencing Elucidates the Origin and Diversification of Allotetraploid Brassica napus

Nature Communications, June 2019

Authors: An H, Qi X, Gaynor ML, Hao Y, Gebken SC, et al.

Brassica napus, an allotetraploid crop, is hypothesized to be a hybrid from unknown varieties of Brassica rapa and Brassica oleracea. Despite the economic importance of B. napus, much is unresolved regarding its phylogenomic relationships, genetic structure, and diversification. Here we conduct a comprehensive study among diverse accessions from 183 B. napus, 112 B. rapa, and 62 B. oleracea and its wild relatives. Using RNA-seq of B. napus accessions, we define the genetic diversity and sub-genome variance of six genetic clusters. This study highlights the complex origin and evolution of B. napus providing insights that can further facilitate B. napus breeding and germplasm preservation.

View Paper

Topological Data Analysis as a Morphometric Method: Using Persistent Homology to Demarcate a Leaf Morphospace

Frontiers in Plant Science, April 2018

Authors: Li M, An H, Angelovici R... Gebken S, et al.

Current morphometric methods that comprehensively measure shape cannot compare the disparate leaf shapes found in seed plants and are sensitive to processing artifacts. We explore the use of persistent homology, a topological method applied as a filtration across simplicial complexes, to overcome these limitations. We apply the method to the analysis of 182,707 leaves, both published and unpublished, representing 141 plant families collected from 75 sites throughout the world. The application of a persistent homology method, using topological features, to measure leaf shape allows for a unified morphometric framework to measure plant form, including shapes, textures, patterns, and branching architectures.

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Fellowships & Grants

Trainee Professional Development Award

November 2025

Society for Neuroscience

Award recognizes undergraduate and graduate students and post baccalaureate and postdoctoral scholars who demonstrate scientific merit and excellence in research. Covers registration and travel stipend.

Spinal Cord Injury/Disease Research Program Grant

April 2025

University of Missouri System

Amount: $100,000

One year of support for research and salary to study translational aberrations because of IGHMBP2 mutations.

Young Investigator Award

February 2024

WORLD Symposium

Chosen as one of 10 investigators to be honored. Covers registration and boarding.

Ruth L. Kirschstein National Research Service Award Individual Predoctoral Fellowship (F31)

April 2023 – May 2024

National Institute of Health: NHLBI

Amount: $27,000

Competitive grant funding two years of research and living expenses.

Precision Medicine Graduate Pathway

July 2021 – May 2023

Washington University in St. Louis

Emphasis in precision medicine upon completion of coursework and clinical partnerships.

Graduate Research Fellowship Program (GRFP)

April 2019 – May 2022

National Science Foundation

Amount: $37,000/year

Competitive fellowship funding three years of financial support.

Travel Grant to Botany 2018

July 2018

American Society of Plant Taxonomists

Chosen as one of 45 students to receive travel support.

Grant in Aid of Research

May 2017 – May 2018

Sigma Xi

Amount: $750

Competitive grant to support research projects.

Ronald E. McNair Scholars

May 2017 – May 2018

University of Missouri – Columbia

Competitive program encouraging minority and first-generation undergraduate students to pursue graduate studies.

Health Careers Opportunity Program (HCOP) Summer Fellowship

May 2017 – August 2017

Johns Hopkins University

Competitive summer fellowship for economically or educationally disadvantaged undergraduate students.

Research Experience for Undergraduates (REU)

May 2016 – August 2016

National Science Foundation

Competitive summer program pairing biological and computational students.

Missouri EPSCoR Summer Fellowship

May 2016 – August 2016

University of Missouri – Columbia

Initiative to support plant centric research in Missouri.

Freshman Research in Plant Science

September 2015 – May 2015

University of Missouri – Columbia

Chosen as one of ten freshmen to be financially supported to conduct research.

Presentations

Oral Presentations

Adenoviral gene therapy for mucopolysaccharidosis type I using the endothelium as a cellular source

February 2024

Rare Disease Day Symposium, St. Louis, MO

Anti-IDUA IgG alters cortical bone structure of mucopolysaccharidoses type I mice treated with intravenous enzyme replacement therapy

February 2024

WORLD Symposium 2024, San Diego, CA

Sarah Hurt, Steven Le, Shih-hsin Kan, Michael Brodt, Patricia Dickson

Adenoviral gene therapy for mucopolysaccharidosis type I using the endothelium as a cellular source

September 2023

Precision Medicine Pathway Retreat, St. Louis, MO

Adenoviral gene therapy for mucopolysaccharidosis type I using the endothelium as a cellular source

May 2023

Gordon Research Seminar on Lysosomal Diseases, Barcelona, Spain

Sarah Hurt, Steven Le, Samir Mendonça, Al Sorensen, Patricia Dickson, David Curiel

Adenoviral Gene Therapy for Mucopolysaccharidoses Type I Using the Endothelium as a Cellular Source

January 2023

Cardiovascular Trainee Research Seminar, St. Louis, MO

Targeted Genome Engineering Using CRISPR/Cas9 in Brassica oleracea

April 2018

29th Annual MU McNair Conference, Columbia, MO

Sarah Gebken, Makenzie E. Mabry, and J. Chris Pires

Poster Presentations

Understanding the function of the IGHMBP2-ABT1 interaction and its role in SMARD1/CMT2S

November 2025

Society for Neuroscience 2025, San Diego, CA

Sarah Hurt, Gangadhar Vadla, Kamlendra Singh, Christian Lorson, Monique Lorson

Understanding the function of the IGHMBP2-ABT1 interaction and its role in SMARD1/CMT2S

May 2025

CVM Research Day, Columbia, MO

Sarah Hurt, Gangadhar Vadla, Monique Lorson, Christian Lorson

Understanding the function of the IGHMBP2-ABT1 interaction and its role in SMARD1/CMT2S

April 2025

MU Show Me Research Week, Columbia, MO

Sarah Hurt, Gangadhar Vadla, Monique Lorson, Christian Lorson

The contribution and therapeutic implications of IGHMBP2 mutations on IGHMBP2 biochemical activity and ABT1 association

February 2025

Rare Disease Day Symposium, St. Louis, MO

Sarah Hurt, Gangadhar Vadla, Monique Lorson, Christian Lorson

Specific antibodies to recombinant human α-L-Iduronidase prevent disease correction in cortical bone in mucopolysaccharidosis type I

May 2024

Musculoskeletal Research Symposium, St. Louis, MO

Sarah Hurt, Steven Le, Shih-hsin Kan, Michael Brodt, and Patricia Dickson

Anti-IDUA IgG alters cortical bone structure of mucopolysaccharidoses type I mice treated with intravenous enzyme replacement therapy

February 2024

Rare Disease Day Symposium, St. Louis, MO

Sarah Hurt, Steven Le, Shih-hsin Kan, Michael Brodt, and Patricia Dickson

Anti-IDUA IgG alters cortical bone structure of mucopolysaccharidoses type I mice treated with intravenous enzyme replacement therapy

February 2024

WORLD Symposium 2024, San Diego, CA

Sarah Hurt, Steven Le, Shih-hsin Kan, Michael Brodt, and Patricia Dickson

Elucidating expression of a corrective enzyme for Mucopolysaccharidosis type I through administration of an adenoviral vector targeted to endothelial cells

February 2024

WORLD Symposium 2024, San Diego, CA

Sarah Hurt, Steven Le, Samir Mendonca, Al Sorensen, David T. Curiel, and Patricia Dickson

Elucidating expression of a corrective enzyme for Mucopolysaccharidosis type I through administration of an adenoviral vector targeted to endothelial cells

November 2023

Ellis Fischel Cancer Center Basic Science Retreat, Innsbrook, MO

Sarah Hurt, Steven Le, Samir Mendonca, Al Sorensen, Patricia Dickson, and David T. Curiel

Elucidating expression of a corrective enzyme for MPS I through administration of an adenoviral vector targeted to endothelial cells

May 2023

Gordon Research Conference on Lysosomal Diseases, Barcelona, Spain

Sarah Hurt, Steven Le, Samir Mendonça, Al Sorensen, Patricia Dickson, and David T. Curiel

Anti-IDUA IgG alters cortical bone structure of mucopolysaccharidosis type I mice treated with intravenous enzyme replacement therapy

May 2023

Musculoskeletal Research Center Symposium 2023, St. Louis, MO

Sarah Hurt, Steven Le, Shih-hsin Kan, Michael Brodt, and Patricia Dickson

Elucidating expression of a corrective enzyme for MPS I through administration of an adenoviral vector targeted to endothelial cells

February 2023

Rare Disease Day Symposium, St. Louis, MO

Sarah Hurt, Steven Le, Samir Mendonça, Al Sorensen, Patricia Dickson, and David T. Curiel

Elucidating expression of a corrective enzyme for MPS I through administration of an adenoviral vector targeted to endothelial cells

February 2023

WORLD Symposium, Orlando, FL

Sarah Hurt, Steven Le, Samir Mendonça, Al Sorensen, Patricia Dickson, and David T. Curiel

Elucidating expression of a corrective enzyme for MPS I through administration of a modified adenoviral vector

September 2022

ISSCR/ASGCT Emerging Therapies, Madison, WI

Sarah Hurt, Steven Le, Samir Mendonça, Al Sorensen, Patricia Dickson, David T. Curiel

An adenoviral mediated gene therapy for mucopolysaccharidosestype I

May 2022

Hope Center for Neurological Disorders Annual Retreat, St. Louis, MO

Sarah Hurt, Steven Le, Samir Mendonça, Paul Boucher, Patricia Dickson, David T. Curiel

An Adenoviral Mediated Gene Therapy for Mucopolysaccharidoses Type I

February 2022

WORLD Symposium, San Diego, CA

Sarah Hurt, Steven Le, Samir Mendonça, Patricia Dickson, and David T. Curiel

Targeted Genome Engineering Using CRISPR/Cas9 in Brassica oleracea

April 2019

MU Undergraduate Research Forum, Columbia, MO

Sarah Gebken, Makenzie E. Mabry, and J. Chris Pires

Targeted Genome Engineering Using CRISPR/Cas9 in Brassica oleracea

April 2019

MU Life Sciences Week, Columbia, MO

Sarah Gebken, Makenzie E. Mabry, and J. Chris Pires

Designing a Detection Device for Viruses

December 2018

Capstone Presentation 2018, Columbia, MO

Ian Heck, Sarah Gebken, Clare Kercher, Robert Rolette and Liqun Gu

Targeted Genome Engineering Using CRISPR/Cas9 in Brassica oleracea

July 2018

Botany 2018, Rochester, MN

Sarah Gebken, Makenzie E. Mabry, and J. Chris Pires

Targeted Genome Engineering Using CRISPR/Cas9 in Brassica oleracea

April 2018

29th Annual MU McNair Conference, Columbia, MO

Sarah Gebken, Makenzie E. Mabry, and J. Chris Pires

Preparing a Genetic Engineering Technique to Bring into the Brassica Crop Plants

April 2018

Council of Undergraduate Research Posters on the Hill, Washington, D.C.

Sarah Gebken, Makenzie E. Mabry, Ruthie Angelovici, and J. Chris Pires

Targeted Genome Engineering Using CRISPR/Cas9 in Brassica oleracea

April 2018

MU Life Sciences Week, Columbia, MO

Sarah Gebken, Makenzie E. Mabry, and J. Chris Pires

Mechanism of Tau Pathological Spreading in a New Mouse Model of Alzheimer’s Disease

September 2017

Beyond the Columns Poster Presentation, Columbia, MO

Sarah Gebken, Kerstin Braunstein, Tong Li, and Philip Wong

Mechanism of Tau Pathological Spreading in a New Mouse Model of Alzheimer’s Disease

July 2017

Johns Hopkins Career, Academic, and Research Experiences for Students (CARES) Symposium, Baltimore, MD

Sarah Gebken, Kerstin Braunstein, Tong Li, and Philip Wong

Implementing CRISPR in Arabidopsis thaliana

May 2017

MU Life Sciences Week, Columbia, MO

Sarah Gebken, Makenzie E. Mabry, J. Chris Pires, Ruthie Angelovici

Preparing a Genetic Engineering Technique to Bring into the Brassica Crop Plants

May 2017

Undergraduate Research Day at the Capitol, Jefferson City, MO

Sarah Gebken, Makenzie E. Mabry, J. Chris Pires, Ruthie Angelovici

Implementing CRISPR in Arabidopsis thaliana

July 2016

Summer Undergraduate Research Forum, Columbia, MO

Sarah Gebken, Makenzie E. Mabry, J. Chris Pires, Ruthie Angelovici